Identification of a novel susceptibility locus for juvenile idiopathic arthritis by genome-wide association analysis

Arthritis Rheum. 2009 Jan;60(1):258-63. doi: 10.1002/art.24179.

Abstract

Objective: Juvenile idiopathic arthritis (JIA) is a chronic rheumatic disease of childhood. Two well-established genetic factors known to contribute to JIA susceptibility, HLA and PTPN22, account for less than half of the genetic susceptibility to disease; therefore, additional genetic factors have yet to be identified. The purpose of this study was to perform a systematic search of the genome to identify novel susceptibility loci for JIA.

Methods: A genome-wide association study using Affymetrix GeneChip 100K arrays was performed in a discovery cohort (279 cases and 184 controls). Single-nucleotide polymorphisms (SNPs) showing the most significant differences between cases and controls were then genotyped in a validation sample of cases (n = 321) and controls, combined with control data from the 1958 UK birth cohort (n = 2,024). In one region in which association was confirmed, fine-mapping was performed (654 cases and 1,847 controls).

Results: Of the 112 SNPs that were significantly associated with JIA in the discovery cohort, 6 SNPs were associated with JIA in the independent validation cohort. The most strongly associated SNP mapped to the HLA region, while the second strongest association was with a SNP within the VTCN1 gene. Fine-mapping of that gene was performed, and 10 SNPs were found to be associated with JIA.

Conclusion: This study is the first to successfully apply a SNP-based genome-wide association approach to the investigation of JIA. The replicated association with markers in the VTCN1 gene defined an additional susceptibility locus for JIA and implicates a novel pathway in the pathogenesis of this chronic disease of childhood.

Publication types

  • Research Support, Non-U.S. Gov't
  • Validation Study

MeSH terms

  • Adolescent
  • Arthritis, Juvenile / genetics*
  • B7-1 Antigen / genetics
  • Chromosome Mapping
  • Genome-Wide Association Study
  • Genomics / methods*
  • Genomics / standards*
  • Genotype
  • HLA Antigens / genetics
  • Humans
  • Oligonucleotide Array Sequence Analysis / standards*
  • Polymorphism, Single Nucleotide
  • Reproducibility of Results
  • Suppression, Genetic
  • V-Set Domain-Containing T-Cell Activation Inhibitor 1

Substances

  • B7-1 Antigen
  • HLA Antigens
  • V-Set Domain-Containing T-Cell Activation Inhibitor 1
  • VTCN1 protein, human